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European Journal of Case Reports in Internal Medicine 2016

Hypoglyceamia in a Patient with a Solitary Fibrous Tumour.

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Andrew Okpe
Kerri Ramsay
Isuru Fernando
Emily Mudenha
Devaka Fernando

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Abstrak

To illustrate an unusual mechanism causing hypoglycaemia.A 76-year-old man presented with episodes of agitation and confusion and was resuscitated with oral glucose gel when found to be hypoglycaemic.A CT scan for an abdominal mass confirmed a solitary fibrous tumour (SFT). The sarcoma multidisciplinary team suggested conservative management. The patient's episodic hypoglycaemia was managed with diet modification including corn-based starch, scheduled snacks and dexamethasone. Glucose levels were within normal range at discharge from hospital. The patient was referred to the palliative care team for follow-up.SFTs causing non-islet cell tumour hypoglycaemia are difficult to treat.To be aware of rarer causes of hypoglycaemia and to consider unusual causes in acute presentations of hypoglycaemia, especially in patients who do not have diabetes.This case illustrates the importance of a thorough general physical and systemic examination, as identifying the abdominal mass is essential to the early diagnosis of this rare condition.Solitary fibrous tumours causing non-islet cell tumour hypoglycaemia are difficult to treat, and even when surgical resections are applicable, recurrence rates are high.

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